Demet ALAYGUT, Arzu BABAYİĞİT, Duygu ÖLMEZ, Nevin UZUNER, Suna ASİLSOY, Handan ÇAKMAKÇI, Özkan KARAMAN

Swyer James Mac Leod sendromlu bir çocuk olgu

Swyer James Mac Leod syndrome is an uncommon and complex disease characterized by roentgenographic hyperlucency of one lung or lobe due to loss of the pulmonary vascular structure. This syndrome seems to be an acquired disease that follows viral bronchiolitis and pneumonitis in childhood. It must be differantiated from many other causes of unilateral lung that is hyperlucent. Most patients with this syndrome can be managed clinically, and whose pathological findings have been described in only a few reports. We describe here a five years old boy with Swyer James Mac Leod syndrome resulting in severe recurrent bronchiolitis.

A pediatric case with Swyer James Mac Leod syndrome

1. Mason RJ, Murray JF, Broaddus VC, Nadel JA, editors Murray and Nadel’s Textbook of Respiratory Medicine, 4th edition. Elsevier-Saunders Philadelphia 2005;312- 359. 2. Hinshaw HC, Murray JF. Diseas of the Chest. 4th Edition. Philadelphia W.B Saunders Co. 1980;588- 589. 3. Fraser RG, Pare JAP, Fraser RS, et al. Diagnosis of the Chest. 3rd edition. Philadelphia W.B Saunders Co. 1990;1969-2275. 4. Fregonese L, Girosi D, Battistini E, et al. Clinical, Physiologic, and Roentgenographic Changes After Pneumonectomy in a Boy With Macleod/Swyer-James Syndrome and Bronchiectasis. Pediatr Pulmon 2002;34:412–416. 5. Fishman AP, ed. Pulmonary Diseas and Disorders. 3rd ed. NewYork, NY: McGraw-Hill;1998;834. 6. Moore ADA, Godwin JD, Dietrich PA, et al. CT findings in eight patients. Am J Resp 1992;58:1211-1215. 7. Chan PW, De Bruyne JA, Goh AY, et al. Swyer James Mac Leod - Mac Leod syndrome. Med J Malaysia 1999; 54:520-522. 8. Mayeux I, Auubry P, Jaunicoux V. Swyer James Mac Leod syndrome or unilateral translucent lung. Med Lav 1993; 84: 387-393. 9. Benzarti M, Jerray M, Mezghemi S, et al. Unilateral hiperlucent lung. Radiology 1998;206:95-101. 10. Arslan N, Ilgan S, Ozkan M, et al. Utility of ventilation and perfusion scan in the diagnosis of young military recruits with an incidental finding of hyperlucent lung. Nucl Med Commun 2001;22:525-530. 11. Hekali P, Halttunen P, Korhola O, et al. Chronic unilateral translucent lung. Aconsecutive series of 40 patiens. Radiographics 1999;19:231-233. 12. Ohri SK, Rutty G, Fountain SW. Acquired segmental emphsema the enlarging spectrum of S.James- Mac Leod syndrome. Ann Thoracic Surg 1993; 56; 120-124. 13. Vishneusky AA, Nikoladse GD. New approchate surgical treatment of S. James syndrome. Ann Thoracic Surg 1990; 50: 130-134. 14. Ökten F, Dilmaç A, Yılmaz F. Bir olgu nedeniyle Swyer James Mac Leod /Macleod sendromu. Solunum Dergisi 1996; 20:607-613.

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1. Mason RJ, Murray JF, Broaddus VC, Nadel JA, editors Murray and Nadel’s Textbook of Respiratory Medicine, 4th edition. Elsevier-Saunders Philadelphia 2005;312- 359.
2. Hinshaw HC, Murray JF. Diseas of the Chest. 4th Edition. Philadelphia W.B Saunders Co. 1980;588- 589.
3. Fraser RG, Pare JAP, Fraser RS, et al. Diagnosis of the Chest. 3rd edition. Philadelphia W.B Saunders Co. 1990;1969-2275.
4. Fregonese L, Girosi D, Battistini E, et al. Clinical, Physiologic, and Roentgenographic Changes After Pneumonectomy in a Boy With Macleod/Swyer-James Syndrome and Bronchiectasis. Pediatr Pulmon 2002;34:412–416.
5. Fishman AP, ed. Pulmonary Diseas and Disorders. 3rd ed. NewYork, NY: McGraw-Hill;1998;834.
6. Moore ADA, Godwin JD, Dietrich PA, et al. CT findings in eight patients. Am J Resp 1992;58:1211-1215.
7. Chan PW, De Bruyne JA, Goh AY, et al. Swyer James Mac Leod - Mac Leod syndrome. Med J Malaysia 1999; 54:520-522.
8. Mayeux I, Auubry P, Jaunicoux V. Swyer James Mac Leod syndrome or unilateral translucent lung. Med Lav 1993; 84: 387-393.
9. Benzarti M, Jerray M, Mezghemi S, et al. Unilateral hiperlucent lung. Radiology 1998;206:95-101.
10. Arslan N, Ilgan S, Ozkan M, et al. Utility of ventilation and perfusion scan in the diagnosis of young military recruits with an incidental finding of hyperlucent lung. Nucl Med Commun 2001;22:525-530.
11. Hekali P, Halttunen P, Korhola O, et al. Chronic unilateral translucent lung. Aconsecutive series of 40 patiens. Radiographics 1999;19:231-233.
12. Ohri SK, Rutty G, Fountain SW. Acquired segmental emphsema the enlarging spectrum of S.James- Mac Leod syndrome. Ann Thoracic Surg 1993; 56; 120-124.
13. Vishneusky AA, Nikoladse GD. New approchate surgical treatment of S. James syndrome. Ann Thoracic Surg 1990; 50: 130-134.
14. Ökten F, Dilmaç A, Yılmaz F. Bir olgu nedeniyle Swyer James Mac Leod /Macleod sendromu. Solunum Dergisi 1996; 20:607-613.