Pulmoner arterden kaynaklanan sol koroner arter anomalisi (ALCAPA) olan 11 yaşında yakınmasız olgu
Pulmoner arterden çıkan anormal sol koroner arter [ Anomalous origin of the Left Coronary Artery from the Pulmonary Artery (ALCAPA)] nadir görülen bir doğuştan kalp anomalisidir. Süt çocukları ve çocuklarda ALCAPA miyokardiyal iskemi veya infarktüsün sık karşılaşılan sebeplerinden birisidir. Bu makalede hastanemize üfürüm duyulması nedeniyle başvuran ve ekokardiyografik olarak dilate kardiomyopati ve kateter-anjiyografisinde sol koroner arterin pulmoner arterden köken aldığı görülen 11 yaşındaki bir hastamız sunulmuştur.
Anomalous left coronary artery from pulmonary artery (ALCAPA) in asymptomatic 11-year-old case
Origin of the left coronary artery from the pulmonary trunk [Anomalous origin of the Left Coronary Artery from the Pulmonary Artery (ALCAPA)] is a rare congenital heart defect. ALCAPA is one of the common causes of myocardial ischemia or infarction in infants and children. In this report, we present an eleven-years-old patient presenting with murmur and accompanied by echocardiographic findings of dilated cardiomyopathy and angiocardiographic investigation that revealed left coronary artery originating from the pulmonary artery.
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- 1. Frommelt PC, Frommelt MA. Congenital coronary artery anomalies. Pediatr Clin North Am 2004; 51: 1273-88.
- 2. Bland EF, White PD, Garland J. Congenital anomalies of the coronary arteries. Am Heart J 1933; 8: 787.
- 3. Chang RR, Allada V. Electrocardiographic and echocardiographic features that distinguish anomalous origin of the left coronary artery from pulmonary artery from idiopathic dilated cardiomyopathy. Pediatr Cardiol 2001; 22: 3-10.
- 4. Khatami AD, Mavroudis C, Backer CL. Anomalous origin of the left coronary artery from the pulmonary artery: collective review of surgical therapy. Ann Thorac Surg 2002; 74: 946-55.
- 5. Schneider S, Rickli H, Giech V, Maeder M. Blind-White Garland syndrome and atrial septal defect-rare association and diagnostic challange. Clin Res Cardiol 2006; 95: 295-300.
- 6. Kostenberger M, Nagel B, Gamillscheg A, Temmel W, Cvirn G, Beitzke A. Myocardial infarction in an adolescent: anomalous origin of the main coronary artery from the right coronary sinus in association with combined prothrombotic defects. Pediatrics 2007; 120: 4247.
- 7. Wilson CL, Dlabal PW, Holeyfield RW, Akins CW, Knauf DG. Anomalous origin of the left coronary artery from the pulmonary artery: case report and review of literature concerning teenagers and adults. J Thorac Cardiovasc Surg 1977; 73: 887-93.
- 8. Singh TP, Di Carli MF, Sullivan NM, Leonen NM, Morrow WR. Myocardial flow reserve in long-term survivors of repair of anomalous left coronary artery from pulmonary artery. J Am Coll Cardiol 1998; 31: 437-43.
- 9. Wesselhoeft IT, Fowcett JS, Johnson AL. Anomalous origin of the left coronary from the pulmonary trunk. Its clinical spectrum, pathology, and pathophysiology, based on a review of 140 cases with seven further cases. Circulation 1968: 38: 403-25.
- 10. Raghuram AR, Krishnan R, Kumar S. Anomalous left coronary artery from pulmonary artery (ALCAPA) in an adult. Interact Cardiovasc Thorac Surg 2004; 20; 213-5.
- 11. Takimura CK, Nakamoto A, Hotta VT, Campos MF, Malamo M, Otsubo R. Anomalous left coronary artery from the pulmonary artery. Report of an adult case. Arq Bras Cardiol 2002; 78: 309-4.
- 12. Fierenes C, Budts W, Denef B, Van de Werf F. A 72 year old women with ALCAPA. Heart 2000; 83: e2: 1-3.
- 13. Jureidini SB, Nouri S, Pennington DG. Anomalous left coronary artery from the pulmonary trunk: repair after diagnostic cross sectional echocardiography. Br Heart J 1987; 58: 173-5.
- 14. Robinson PJ, Sullivan ID, Kumpeng V, Anderson RH, Macartney FJ. Anomalous origin of the left coronary artery from the pulmonary trunk: potential for false negative diagnosis with cross sectional echocardiography. Br Heart J 1984; 52: 272-7.
- 15. Amanullah MM, Hamilton JRL, Hasan A. Anomalous left coronary artery from the pulmonary artery: creating an autogenous arterial conduit for aortic implantation. Eur J Cardiothorac Surg 2001; 20: 853-5.
- 16. Vouhe PR, Baillot-Vernant F, Trinquet F, et al. Anomalous left coronary artery from the pulmonary artery in infants. Which operation? When? J Thorac Cardiovasc Surg 1987; 94: 192-9.