Testicular microlithiasis is an uncommon abnormality in which concentric laminated bodies aré scattered throughout the testis within seminiferous tubules. The condition can be seen in one or two of the testes (1- 22). It has been associated most commonly with cryptorchidism (1-9), infertility (5-9), and testicular neoplasms (8-15). The clinical and ultrasonographic findings of a testicular microlithiasis case with hypogonadism are described. We also review the relevant literature.